下顎骨骨髄炎を契機に60歳で診断された濃化異骨症の1例 A case of pycnodysostosis diagnosed on the dection of mandibular osteomyelitis in a 60-year-old petient

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Pycnodysostosis is a rare autosomal recessive skeletal dysplasia characterized by short-limbed dwarfism, acroosteolysis, and a specific facial appearance associated with dysplasia of the jaw. We report the treatment of osteomyelitis of the mandible in a patient with pycnodysostosis that had not been diagnosed until 60 years of age. The patient visited our department because of buccal phlegmon arising from mandibular osteomyelitis. Pycnodysostosis was diagnosed on the basis of osteomyelitis of the jaw and other physical findings. He was treated under hospitalization. First, anti-inflammatory treatment of the right buccal phlegmon was performed. Subsequently, sequestrectomy was performed, and an external dental fistula was simultaneously constructed using the rhomboid-to-W technique. There has been no recurrence of acute inflammation, and the postoperative course has been favorable up to the present (2 years 10 months after operation). However, the patient is being very closely followed up because the formation of a new sequestrum.

Pycnodysostosis is a rare autosomal recessive skeletal dysplasia characterized by short-limbed dwarfism, acroosteolysis, and a specific facial appearance associated with dysplasia of the jaw. We report the treatment of osteomyelitis of the mandible in a patient with pycnodysostosis that had not been diagnosed until 60 years of age. The patient visited our department because of buccal phlegmon arising from mandibular osteomyelitis. Pycnodysostosis was diagnosed on the basis of osteomyelitis of the jaw and other physical findings. He was treated under hospitalization. First, anti-inflammatory treatment of the right buccal phlegmon was performed. Subsequently, sequestrectomy was performed, and an external dental fistula was simultaneously constructed using the rhomboid-to-W technique. There has been no recurrence of acute inflammation, and the postoperative course has been favorable up to the present (2 years 10 months after operation). However, the patient is being very closely followed up because the formation of a new sequestrum.

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  • 日本口腔外科学会雑誌

    日本口腔外科学会雑誌 57(7), 414-418, 2011-07-20

    社団法人 日本口腔外科学会

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各種コード

  • NII論文ID(NAID)
    10030272511
  • NII書誌ID(NCID)
    AN00189163
  • 本文言語コード
    JPN
  • 資料種別
    NOT
  • ISSN
    00215163
  • NDL 記事登録ID
    11189521
  • NDL 雑誌分類
    ZS44(科学技術--医学--歯科学・口腔外科学)
  • NDL 請求記号
    Z19-145
  • データ提供元
    CJP書誌  NDL  J-STAGE 
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